Genetic Information

Gene & Transcript Details

Gene
TP53
Transcript
NM_000546.6 MANE Select
Total Exons
Reference Sequence
NC_000017.10
Alternative Transcripts
IDStatusDetails
NM_000546.5 RefSeq Select 2591 nt | 203–1384
NM_000546.3 Alternative 2640 nt | 252–1433
NM_000546.6 MANE Select 2512 nt | 143–1324
NM_000546.4 Alternative 2586 nt | 198–1379
NM_000546.2 Alternative 2629 nt | 252–1433

Variant Details

HGVS Notation
NM_000546.6:c.215_216delinsGT
Protein Change
P72R
Location
Exon 4 (Exon 4 of )
4
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.0 in 100,000
Extremely Rare
ACMG Criteria Applied PM2
This variant is absent or extremely rare in population databases (PM2 criteria applies).

ClinVar

Open
Classification
Likely Benign
2 publications
Publications List
PMID: 17606709

Variant summary: TP53 c.215_216delinsGT (p.Pro72Arg) results in a non-conservative amino acid change in the encoded protein sequence. Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change. This variant was found in 3/120822 control chromosomes at a frequency of 0.0000248, which does not exceed the estimated maximal expected allele frequency of a pathogenic TP53 variant (0.0000398). However, the variant c.215C>G alone, which leads to the same Pro72Arg missense change, is found at a very high frequency in the population (79805/120924 control chromosomes; 27306 homozygotes), which strongly suggests that the Pro72Arg change does not affect protein function. ClinVar contains an entry for this variant (Variation ID: 237944). Based on the evidence outlined above, the variant was classified as likely benign.

Clinical Statement

"This variant has been reported in ClinVar as Likely benign (6 clinical laboratories) and as Benign (1 clinical laboratories)."

COSMIC Somatic Evidence

Open
COSMIC ID
COSM7410556
Recurrence
1 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
COSMIC Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene TP53.

Functional Studies & Therapeutic Relevance

Functional Summary

The TP53 P72R variant has been functionally studied and shown to decrease Pgc-1a binding, increase mitochondrial function, and enhance migration, invasion, and metastasis in the presence of mutant TP53 in cell culture and mouse models. However, it also transactivates downstream target genes and inhibits cell growth similarly to wild-type TP53 in culture. Thus, the overall effect of the P72R variant on TP53 protein function remains unclear.

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Mixed/VUS
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.0 -85 bp
- Donor Loss (DL) 0.04 41 bp
+ Acceptor Gain (AG) 0.0 100 bp
+ Donor Gain (DG) 0.0 -159 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
PVS1

PVS1 (Not Applied)

According to VCEP guidelines, PVS1 applies to null variants predicted to undergo NMD or disrupt critical splice sites. The evidence for this variant shows: it is a missense change (p.P72R), not a null or canonical splice variant. Therefore, this criterion is not applied.

PS1

PS1 (Not Applied)

According to VCEP guidelines, PS1 applies to a variant causing the same amino acid change as a known pathogenic variant. The evidence for this variant shows: no other pathogenic p.P72R variant reported. Therefore, this criterion is not applied.

PS2

PS2 (Not Applied)

According to standard ACMG guidelines, PS2 applies to confirmed de novo variants with parental confirmation. The evidence for this variant shows: no de novo data available. Therefore, this criterion is not applied.

PS3

PS3 (Not Applied)

According to VCEP guidelines, PS3 Strong requires non-functional Kato data AND LOF on another assay. The evidence for this variant shows: functional studies are conflicting with overall preserved TP53 transactivation. Therefore, this criterion is not applied.

PS4

PS4 (Not Applied)

According to VCEP guidelines, PS4 requires quantitative case–control or proband point scoring. The evidence for this variant shows: no case enrichment data available. Therefore, this criterion is not applied.

PM1

PM1 (Not Applied)

According to VCEP guidelines, PM1 Moderate applies to missense variants at TP53 hotspots codons 175, 245, 248, 249, 273, or 282. The evidence for this variant shows: it is at codon 72, outside these hotspots. Therefore, this criterion is not applied.

PM2

PM2 (Not Applied)

According to VCEP guidelines, PM2 Supporting applies when the allele frequency is <0.00003 in gnomAD. The evidence for this variant shows: allele frequency ∼0.3 in gnomAD. Therefore, this criterion is not applied.

PM3

PM3 (Not Applied)

According to standard ACMG guidelines, PM3 applies to variants observed in trans with a pathogenic variant in recessive disorders. The evidence for this variant shows: TP53 disease is dominant and no trans observations reported. Therefore, this criterion is not applied.

PM4

PM4 (Not Applied)

According to standard ACMG guidelines, PM4 applies to protein length changes via in‐frame indels. The evidence for this variant shows: it is a missense substitution (p.P72R), not an in‐frame indel. Therefore, this criterion is not applied.

PM5

PM5 (Not Applied)

According to VCEP guidelines, PM5 applies to missense variants at a residue with ≥2 pathogenic changes (Strong) or 1 pathogenic change (Moderate). The evidence for this variant shows: no other pathogenic missense at codon 72. Therefore, this criterion is not applied.

PM6

PM6 (Not Applied)

According to standard ACMG guidelines, PM6 applies to assumed de novo cases without confirmation. The evidence for this variant shows: no de novo data available. Therefore, this criterion is not applied.

PP1

PP1 (Not Applied)

According to VCEP guidelines, PP1 Supporting requires cosegregation in 3–4 meioses; Moderate requires 5–6; Strong requires ≥7. The evidence for this variant shows: no family segregation data. Therefore, this criterion is not applied.

PP2

PP2 (Not Applied)

According to standard ACMG guidelines, PP2 applies when missense variants in a gene with low benign variation and pathogenic missense are common. The evidence for this variant shows: TP53 has many tolerated missense variants. Therefore, this criterion is not applied.

PP3

PP3 (Not Applied)

According to standard ACMG guidelines, PP3 applies when multiple computational tools predict a deleterious effect. The evidence for this variant shows: computational tools predict benign. Therefore, this criterion is not applied.

PP4

PP4 (Not Applied)

According to VCEP guidelines, PP4 applies with phenotype specificity and variant observation. The evidence for this variant shows: no phenotype data. Therefore, this criterion is not applied.

PP5

PP5 (Not Applied)

According to standard ACMG guidelines, PP5 applies when a reputable source reports a pathogenic assertion. The evidence for this variant shows: no pathogenic assertions. Therefore, this criterion is not applied.

BA1

BA1 (Stand Alone)

According to VCEP guidelines, BA1 Stand Alone applies when the filtering allele frequency ≥0.001 in gnomAD. The evidence for this variant shows: allele frequency ∼0.3 in gnomAD, well above the 0.001 threshold. Therefore, this criterion is applied at Stand Alone strength because the variant is a common polymorphism inconsistent with pathogenicity.

BS1

BS1 (Not Applied)

According to VCEP guidelines, BS1 Strong applies when the filtering allele frequency is ≥0.0003 but <0.001. The evidence for this variant shows: allele frequency ∼0.3, which exceeds the upper limit. Therefore, this criterion is not applied.

BS2

BS2 (Not Applied)

According to VCEP guidelines, BS2 Strong applies when ≥8 unrelated elderly females without cancer carry the variant. The evidence for this variant shows: no such data. Therefore, this criterion is not applied.

BS3

BS3 (Not Applied)

According to VCEP guidelines, BS3 Strong applies when functional assays demonstrate no loss of function. The evidence for this variant shows: functional studies are conflicting with some evidence of altered binding. Therefore, this criterion is not applied.

BS4

BS4 (Not Applied)

According to VCEP guidelines, BS4 applies to lack of segregation in affected family members. The evidence for this variant shows: no family data. Therefore, this criterion is not applied.

BP1

BP1 (Not Applied)

According to standard ACMG guidelines, BP1 applies when missense variants occur in a gene where only truncating variants cause disease. The evidence for this variant shows: TP53 pathogenic missense are common. Therefore, this criterion is not applied.

BP2

BP2 (Not Applied)

According to standard ACMG guidelines, BP2 applies when observed in trans with pathogenic variant for dominant disorders. The evidence for this variant shows: no such observations. Therefore, this criterion is not applied.

BP3

BP3 (Not Applied)

According to standard ACMG guidelines, BP3 applies to in‐frame deletions/insertions in repetitive regions. The evidence for this variant shows: it is a missense substitution. Therefore, this criterion is not applied.

BP4

BP4 (Supporting)

According to standard ACMG guidelines, BP4 applies when multiple computational tools predict no impact. The evidence for this variant shows: PolyPhen benign and SpliceAI 0.04 indicating no splicing impact. Therefore, this criterion is applied at Supporting strength because computational evidence supports benign effect.

BP5

BP5 (Not Applied)

According to standard ACMG guidelines, BP5 applies when a variant is found in trans with a pathogenic variant in a dominant disorder. The evidence for this variant shows: no such finding. Therefore, this criterion is not applied.

BP6

BP6 (Supporting)

According to standard ACMG guidelines, BP6 applies when a reputable source reports a benign assertion without available evidence. The evidence for this variant shows: ClinVar entries by multiple laboratories classify it as Likely benign/Benign. Therefore, this criterion is applied at Supporting strength.

BP7

BP7 (Not Applied)

According to VCEP guidelines, BP7 applies to synonymous or intronic variants outside splice motifs. The evidence for this variant shows: it is a missense change. Therefore, this criterion is not applied.