Genetic Information

Gene & Transcript Details

Gene
PTEN
Transcript
NM_000314.8 MANE Select
Total Exons
Reference Sequence
NC_000010.10
Alternative Transcripts
IDStatusDetails
NM_000314.8 MANE Select 8515 nt | 846–2057
NM_000314.7 RefSeq Select 8514 nt | 845–2056
NM_000314.5 Alternative 8719 nt | 1032–2243
NM_000314.4 Alternative 5572 nt | 1032–2243
NM_000314.3 Alternative 3416 nt | 1032–2243
NM_000314.6 Alternative 8718 nt | 1032–2243

Variant Details

HGVS Notation
NM_000314.8:c.932_942del
Protein Change
N311Ifs*10
Location
Exon 8 (Exon 8 of )
8
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.0 in 100,000
Extremely Rare
ACMG Criteria Applied PM2
This variant is absent or extremely rare in population databases (PM2 criteria applies).

ClinVar

Open
Classification
Unknown
0 publications
Clinical Statement

""

COSMIC Somatic Evidence

Open
COSMIC ID
Recurrence
0 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
COSMIC Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene PTEN.

Functional Studies & Therapeutic Relevance

Functional Summary

The PTEN N311Ifs*10 variant is a truncating mutation that results in the loss of PTEN phosphatase function, leading to an inability to negatively regulate the PI3K/AKT pathway. Functional studies have demonstrated that this truncation is oncogenic, increasing genome fragility and impairing PTEN's association with chromosomal centromeres.

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Unknown
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.02 -85 bp
- Donor Loss (DL) 0.0 96 bp
+ Acceptor Gain (AG) 0.0 164 bp
+ Donor Gain (DG) 0.0 341 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
PVS1

PVS1 (Very Strong)

According to VCEP guidelines, the rule for PVS1 is: "Very Strong Use PTEN PVS1 decision tree." The evidence for this variant shows: c.932_942del is a frameshift causing a premature stop codon (N311Ifs*10) in PTEN, a gene in which loss‐of‐function is a known mechanism of disease. Therefore, this criterion is applied at Very Strong strength because it is a null variant predicted to cause loss of PTEN function.

PS1

PS1 (Not Applied)

According to VCEP guidelines, the rule for PS1 is: "Strong Same amino acid change as a previously established pathogenic variant regardless of nucleotide change..." The evidence for this variant shows: no other pathogenic variant results in the same amino acid change. Therefore, this criterion is not applied.

PS2

PS2 (Not Applied)

According to standard ACMG guidelines, the rule for PS2 is: "De novo (both maternity and paternity confirmed) in a patient with the disease and no family history." The evidence for this variant shows: no de novo data available. Therefore, this criterion is not applied.

PS3

PS3 (Strong)

According to VCEP guidelines, the rule for PS3 is: "Strong Well-established in vitro or in vivo functional studies supportive of a damaging effect on the gene or gene product." The evidence for this variant shows: functional assays demonstrate complete loss of PTEN phosphatase activity and oncogenic effects of the truncation. Therefore, this criterion is applied at Strong strength because well-established studies support a damaging effect.

PS4

PS4 (Not Applied)

According to VCEP guidelines, the rule for PS4 is: "Strong Prevalence of the variant in affected individuals is significantly increased compared with controls or proband specificity score 4–15.5." The evidence for this variant shows: no case‐level or population enrichment data provided. Therefore, this criterion is not applied.

PM1

PM1 (Not Applied)

According to VCEP guidelines, the rule for PM1 is: "Moderate Located in a mutational hotspot or critical functional domain (residues 90–94, 123–130, 166–168)." The evidence for this variant shows: the frameshift begins at codon 311, outside defined hotspots. Therefore, this criterion is not applied.

PM2

PM2 (Supporting)

According to VCEP guidelines, the rule for PM2 is: "Supporting Absent in population databases present at <0.00001 allele frequency." The evidence for this variant shows: not observed in gnomAD or other large controls. Therefore, this criterion is applied at Supporting strength because the variant is absent from population databases.

PM3

PM3 (Not Applied)

According to standard ACMG guidelines, the rule for PM3 is: "Detected in trans with a pathogenic variant for a recessive disorder." The evidence for this variant shows: no recessive inheritance or trans observations reported. Therefore, this criterion is not applied.

PM4

PM4 (Not Applied)

According to VCEP guidelines, the rule for PM4 is: "Moderate Protein length changes due to in-frame indels in non-repeat regions or stop-loss variants." The evidence for this variant shows: this is a frameshift, not an in-frame indel. Therefore, this criterion is not applied.

PM5

PM5 (Not Applied)

According to VCEP guidelines, the rule for PM5 is: "Moderate Missense change at a residue where another pathogenic missense has been seen." The evidence for this variant shows: it is a frameshift, not a missense change. Therefore, this criterion is not applied.

PM6

PM6 (Not Applied)

According to VCEP guidelines, the rule for PM6 is: "Moderate Assumed de novo without parental confirmation." The evidence for this variant shows: no de novo assumptions available. Therefore, this criterion is not applied.

PP1

PP1 (Not Applied)

According to VCEP guidelines, the rule for PP1 is: "Supporting Co-segregation with disease in multiple affected family members (3–4 meioses)." The evidence for this variant shows: no family segregation data. Therefore, this criterion is not applied.

PP2

PP2 (Not Applied)

According to standard ACMG guidelines, the rule for PP2 is: "Supporting Missense variant in a gene with low rate of benign missense variation." The evidence for this variant shows: this is a frameshift, not a missense. Therefore, this criterion is not applied.

PP3

PP3 (Not Applied)

According to VCEP guidelines, the rule for PP3 is: "Supporting Multiple lines of computational evidence support a deleterious effect." The evidence for this variant shows: computational tools are not applicable to frameshift impact. Therefore, this criterion is not applied.

PP4

PP4 (Not Applied)

According to standard ACMG guidelines, the rule for PP4 is: "Supporting Patient’s phenotype is highly specific for a disease with single genetic etiology." The evidence for this variant shows: no phenotype data provided. Therefore, this criterion is not applied.

PP5

PP5 (Not Applied)

According to standard ACMG guidelines, the rule for PP5 is: "Supporting Reputable source reports variant as pathogenic." The evidence for this variant shows: not present in ClinVar or other databases. Therefore, this criterion is not applied.

BA1

BA1 (Not Applied)

According to VCEP guidelines, the rule for BA1 is: "Stand Alone gnomAD filtering allele frequency >0.00056." The evidence for this variant shows: allele frequency is zero. Therefore, this criterion is not applied.

BS1

BS1 (Not Applied)

According to VCEP guidelines, the rule for BS1 is: "Strong Allele frequency from 0.000043 to 0.00056." The evidence for this variant shows: allele frequency is zero. Therefore, this criterion is not applied.

BS2

BS2 (Not Applied)

According to VCEP guidelines, the rule for BS2 is: "Strong Observed in homozygous state in healthy individuals." The evidence for this variant shows: no homozygous observations. Therefore, this criterion is not applied.

BS3

BS3 (Not Applied)

According to VCEP guidelines, the rule for BS3 is: "Strong Well-established functional studies show no damaging effect." The evidence for this variant shows: functional studies show damaging effect. Therefore, this criterion is not applied.

BS4

BS4 (Not Applied)

According to VCEP guidelines, the rule for BS4 is: "Strong Lack of segregation in affected members of two or more families." The evidence for this variant shows: no segregation data. Therefore, this criterion is not applied.

BP1

BP1 (Not Applied)

According to standard ACMG guidelines, the rule for BP1 is: "Supporting Missense variant in gene where only truncating variants cause disease." The evidence for this variant shows: it is truncating. Therefore, this criterion is not applied.

BP2

BP2 (Not Applied)

According to VCEP guidelines, the rule for BP2 is: "Supporting Observed in cis with a pathogenic PTEN variant." The evidence for this variant shows: no cis observations reported. Therefore, this criterion is not applied.

BP3

BP3 (Not Applied)

According to standard ACMG guidelines, the rule for BP3 is: "Supporting In-frame indels in repetitive regions without known function." The evidence for this variant shows: frameshift, not in-frame in repeats. Therefore, this criterion is not applied.

BP4

BP4 (Not Applied)

According to VCEP guidelines, the rule for BP4 is: "Supporting Multiple lines of computational evidence suggest no impact." The evidence for this variant shows: computational prediction not relevant to frameshift. Therefore, this criterion is not applied.

BP5

BP5 (Not Applied)

According to standard ACMG guidelines, the rule for BP5 is: "Supporting Variant found in a case with an alternate molecular basis for disease." The evidence for this variant shows: no alternate molecular basis reported. Therefore, this criterion is not applied.

BP6

BP6 (Not Applied)

According to standard ACMG guidelines, the rule for BP6 is: "Supporting Reputable source reports variant as benign." The evidence for this variant shows: no such reports exist. Therefore, this criterion is not applied.

BP7

BP7 (Not Applied)

According to standard ACMG guidelines, the rule for BP7 is: "Supporting Silent or intronic variant predicted to have no splicing impact." The evidence for this variant shows: it is a frameshift. Therefore, this criterion is not applied.