Genetic Information

Gene & Transcript Details

Gene
ATM
Transcript
NM_000051.4 MANE Select
Total Exons
Reference Sequence
NC_000011.9
Alternative Transcripts
IDStatusDetails
NM_000051.3 RefSeq Select 13147 nt | 386–9556
NM_000051.4 MANE Select 12915 nt | 151–9321

Variant Details

HGVS Notation
NM_000051.4:c.8395_8404del
Protein Change
F2799Kfs*4
Location
Exon 57 (Exon 57 of )
57
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.00199 in 100,000
Extremely Rare
ACMG Criteria Applied PM2
This variant is absent or extremely rare in population databases (PM2 criteria applies).

ClinVar

Open
Classification
Unknown
0 publications
Clinical Statement

""

COSMIC Somatic Evidence

Open
COSMIC ID
COSM6213119
Recurrence
6 occurrences
PM1 Criteria
Not Applied

Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene ATM.

Functional Studies & Therapeutic Relevance

Functional Summary

The ATM F2799Kfs*4 variant is a truncating mutation in the ATM gene, which is a tumor suppressor involved in the DNA damage response. Functional studies indicate that truncating mutations in ATM can lead to the production of C-terminally truncated proteins, resulting in decreased DNA repair efficiency and increased cellular motility. These effects support the conclusion that the ATM F2799Kfs*4 variant is likely oncogenic.

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Unknown
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.0 141 bp
- Donor Loss (DL) 0.0 -55 bp
+ Acceptor Gain (AG) 0.02 -115 bp
+ Donor Gain (DG) 0.07 34 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
PVS1

PVS1 (Very Strong)

According to VCEP guidelines: the rule for PVS1 is: "Very Strong Strength: Very Strong Use ATM PVS1 Decision Tree Modification Type: Gene-specific,Strength". The evidence for this variant shows a frameshift leading to a premature stop codon (F2799Kfs*4), predicted to undergo NMD in a gene where LOF is a known disease mechanism and not in the last exon. Therefore, this criterion is applied at Very Strong strength because it meets the VCEP gene-specific decision tree for truncating variants in ATM.

PS1

PS1 (Not Applied)

According to standard ACMG guidelines: PS1 applies when the same amino acid change as a known pathogenic variant is observed. The evidence for this variant shows a novel frameshift rather than a known missense change. Therefore, PS1 is not applied.

PS2

PS2 (Not Applied)

According to standard ACMG guidelines: PS2 applies for confirmed de novo occurrence with maternity and paternity confirmed. No parental testing data are available for this variant. Therefore, PS2 is not applied.

PS3

PS3 (Not Applied)

According to VCEP guidelines: PS3 requires functional rescue assays specific to ATM, with moderate strength if both target phosphorylation and radiosensitivity rescue fail, or supporting strength if only phosphorylation rescue fails. The evidence describes generic truncation effects without rescue experiments. Therefore, PS3 is not applied.

PS4

PS4 (Not Applied)

According to standard ACMG guidelines: PS4 applies when there is significant statistical evidence from case-control studies (OR ≥2, p≤0.05). No case-control data are provided. Therefore, PS4 is not applied.

PM1

PM1 (Not Applied)

According to standard ACMG guidelines: PM1 applies to variants located in mutational hot spots or critical functional domains. No domain or hotspot information is provided for this residue. Therefore, PM1 is not applied.

PM2

PM2 (Not Applied)

According to VCEP guidelines: PM2_Supporting applies for frequency ≤0.001% if n=1. The evidence shows MAF=0.00199% (5/251232 alleles), above the VCEP threshold. Therefore, PM2 is not applied.

PM3

PM3 (Not Applied)

According to VCEP guidelines: PM3 applies to recessive disorders when a variant is detected in trans with a pathogenic variant. No allelic configuration data are available. Therefore, PM3 is not applied.

PM4

PM4 (Not Applied)

According to standard ACMG guidelines: PM4 applies to protein length changes due to in-frame indels or stop-loss variants. This is a frameshift leading to stop gain, which is covered by PVS1, not PM4. Therefore, PM4 is not applied.

PM5

PM5 (Supporting)

According to VCEP guidelines: PM5_Supporting applies to truncating variants with PTC upstream of p.R3047. The variant F2799Kfs*4 introduces a stop codon upstream of p.R3047. Therefore, PM5 is applied at Supporting strength as per gene-specific rule.

PM6

PM6 (Not Applied)

According to standard ACMG guidelines: PM6 applies to assumed de novo variants without confirmation of maternity/paternity. No de novo data are available. Therefore, PM6 is not applied.

PP1

PP1 (Not Applied)

According to standard ACMG guidelines: PP1 applies with segregation data. No family segregation information is provided. Therefore, PP1 is not applied.

PP2

PP2 (Not Applied)

According to standard ACMG guidelines: PP2 applies to missense variants in genes with low benign missense variation. This is a truncating variant. Therefore, PP2 is not applied.

PP3

PP3 (Not Applied)

According to VCEP guidelines: PP3 applies when REVEL >0.7333 or strong splicing prediction. No REVEL score or significant splicing impact is present. Therefore, PP3 is not applied.

PP4

PP4 (Not Applied)

According to standard ACMG guidelines: PP4 applies when patient phenotype is highly specific for a single gene. No phenotype data are provided. Therefore, PP4 is not applied.

PP5

PP5 (Not Applied)

According to standard ACMG guidelines: PP5 applies when a reputable source classifies the variant as pathogenic. The variant is not found in ClinVar or other databases. Therefore, PP5 is not applied.

BA1

BA1 (Not Applied)

According to standard ACMG guidelines: BA1 applies for allele frequency >5%. The observed MAF is 0.00199%. Therefore, BA1 is not applied.

BS1

BS1 (Not Applied)

According to standard ACMG guidelines: BS1 applies for allele frequency >1% (disease-specific threshold). The MAF is well below that. Therefore, BS1 is not applied.

BS2

BS2 (Not Applied)

According to standard ACMG guidelines: BS2 applies when observed in healthy individuals. No such data are reported. Therefore, BS2 is not applied.

BS3

BS3 (Not Applied)

According to VCEP guidelines: BS3 applies when variant rescues ATM-specific functional assays. No rescue data are available. Therefore, BS3 is not applied.

BS4

BS4 (Not Applied)

According to standard ACMG guidelines: BS4 applies for lack of segregation in affected family members. No non-segregation data exist. Therefore, BS4 is not applied.

BP1

BP1 (Not Applied)

According to standard ACMG guidelines: BP1 applies to missense variants in a gene where only LOF causes disease. This is a LOF variant. Therefore, BP1 is not applied.

BP2

BP2 (Not Applied)

According to VCEP guidelines: BP2 applies to variants in trans with a pathogenic variant in recessive disease. No such data. Therefore, BP2 is not applied.

BP3

BP3 (Not Applied)

According to standard ACMG guidelines: BP3 applies to in-frame indels in repetitive regions. This is a frameshift. Therefore, BP3 is not applied.

BP4

BP4 (Not Applied)

According to VCEP guidelines: BP4 applies when REVEL ≤0.249 or benign splice prediction. No computational benign evidence is available. Therefore, BP4 is not applied.

BP5

BP5 (Not Applied)

According to standard ACMG guidelines: BP5 applies when variant found in a case with an alternate molecular cause. No alternate cause has been documented. Therefore, BP5 is not applied.

BP6

BP6 (Not Applied)

According to standard ACMG guidelines: BP6 applies when a reputable source classifies the variant as benign. No such assertion exists. Therefore, BP6 is not applied.

BP7

BP7 (Not Applied)

According to standard ACMG guidelines: BP7 applies to synonymous or deep intronic variants with no splicing impact. This is a frameshift. Therefore, BP7 is not applied.