Genetic Information

Gene & Transcript Details

Gene
BRIP1
Transcript
NM_032043.3 MANE Select
Total Exons
Reference Sequence
NC_000017.10
Alternative Transcripts
IDStatusDetails
NM_032043.2 RefSeq Select 8166 nt | 307–4056
NM_032043.1 Alternative 4563 nt | 142–3891
NM_032043.3 MANE Select 8182 nt | 276–4025

Variant Details

HGVS Notation
NM_032043.3:c.3069C>T
Protein Change
L1023=
Location
Exon 20 (Exon 20 of )
20
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.0106 in 100,000
Extremely Rare
ACMG Criteria Applied PM2
This variant is absent or extremely rare in population databases (PM2 criteria applies).

ClinVar

Open
Classification
Likely Benign
2 publications
Publications List
PMID: 31214711

Curator: Arleen D. Auerbach. Submitter to LOVD: Yukihide Momozawa.

Clinical Statement

"This variant has been reported in ClinVar as Likely benign (8 clinical laboratories) and as Benign (3 clinical laboratories)."

COSMIC Somatic Evidence

Open
COSMIC ID
Recurrence
0 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
COSMIC Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene BRIP1.

Functional Studies & Therapeutic Relevance

Functional Summary

Error in OpenAI Consolidation. OncoKB: BRIP1L1023=BRIP1L1023=SomaticNCBI Gene:83990|Show additional gene information Variant OverviewBRIP1, a DEAH helicase, is altered by mutation and amplification in various cancers, including breast cancer and melanoma.This is a synonymous mutation and is not annotated by OncoKB. JAX-CKB: No results found

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Mixed/VUS
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.01 163 bp
- Donor Loss (DL) 0.0 -252 bp
+ Acceptor Gain (AG) 0.0 154 bp
+ Donor Gain (DG) 0.0 29 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
PM2

PM2 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

BP4

BP4 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

BP6

BP6 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)