Genetic Information

Gene & Transcript Details

Gene
LZTR1
Transcript
NM_006767.4 MANE Select
Total Exons
Reference Sequence
NC_000022.10
Alternative Transcripts
IDStatusDetails
NM_006767.3 Alternative 4332 nt | 104–2626
NM_006767.4 MANE Select 4282 nt | 76–2598
NM_006767.2 Alternative 4234 nt | 6–2528

Variant Details

HGVS Notation
NM_006767.4:c.2219+13C>T
Protein Change
?
Location
Exon 18 (Exon 18 of )
18
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
1.0 in 100,000
Extremely Rare
ACMG Criteria Applied BS1

ClinVar

Open
Classification
Likely Benign
2 publications
Clinical Statement

"This variant has been reported in ClinVar as Benign (8 clinical laboratories) and as Likely benign (1 clinical laboratories)."

COSMIC Somatic Evidence

Open
COSMIC ID
COSN31945036
Recurrence
4 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
COSMIC Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene LZTR1.

Functional Studies & Therapeutic Relevance

Functional Summary

Error in OpenAI Consolidation. OncoKB: LZTR12219+13C>TLZTR12219+13C>TSomaticNCBI Gene:8216|Show additional gene information Variant OverviewLZTR1, a ubiquitin ligase adaptor protein, is recurrently altered by mutation in glioblastoma, Noonan syndrome, and schwannomatosis.The LZTR1 2219+13c>T mutation has not specifically been reviewed by the OncoKB team, and therefore its biological significance is unknown. JAX-CKB: No results found

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Mixed/VUS
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.0 -397 bp
- Donor Loss (DL) 0.12 -39 bp
+ Acceptor Gain (AG) 0.01 -124 bp
+ Donor Gain (DG) 0.05 15 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
BP4

BP4 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

BP6

BP6 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)