Genetic Information

Gene & Transcript Details

Gene
MLH3
Transcript
NM_001040108.2 MANE Select
Total Exons
Reference Sequence
NC_000014.8
Alternative Transcripts
IDStatusDetails
NM_001040108.2 MANE Select 7820 nt | 152–4513
NM_001040108.1 RefSeq Select 7911 nt | 217–4578

Variant Details

HGVS Notation
NM_001040108.2:c.3488G>A
Protein Change
G1163D
Location
Exon 5 (Exon 5 of )
5
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.213 in 100,000
Extremely Rare
ACMG Criteria Applied None

ClinVar

Open
Classification
Uncertain Significance (VUS)
2 publications
Clinical Statement

"This variant has been reported in ClinVar as Uncertain significance (2 clinical laboratories) and as Benign (6 clinical laboratories)."

COSMIC Somatic Evidence

Open
COSMIC ID
COSM9995595
Recurrence
2 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
COSMIC Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene MLH3.

Functional Studies & Therapeutic Relevance

Functional Summary

Error in OpenAI Consolidation. OncoKB: MLH3G1163DMLH3G1163DSomaticNCBI Gene:27030|Show additional gene information Variant OverviewMLH3, a DNA mismatch repair protein, is infrequently altered in cancer.The MLH3 G1163D mutation has not specifically been reviewed by the OncoKB team, and therefore its biological significance is unknown. JAX-CKB: No results found

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Mixed/VUS
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.0 449 bp
- Donor Loss (DL) 0.0 22 bp
+ Acceptor Gain (AG) 0.11 22 bp
+ Donor Gain (DG) 0.02 -82 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
BP4

BP4 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)