Genetic Information

Gene & Transcript Details

Gene
BRCA2
Transcript
NM_000059.3 MANE Select
Total Exons
Reference Sequence
NC_000013.10
Alternative Transcripts
IDStatusDetails
NM_000059.4 MANE Select 11954 nt | 200–10456
NM_000059.2 Alternative 11386 nt | 228–10484
NM_000059.3 RefSeq Select 11386 nt | 228–10484

Variant Details

HGVS Notation
NM_000059.3:c.8362T>C
Protein Change
W2788R
Location
Exon 19 (Exon 19 of )
19
5'Exon Structure3'
Functional Consequence
Loss of Function
Alternate Identifiers

Clinical & Population Data

Population Frequency

gnomAD
Global Frequency
0.0 in 100,000
Extremely Rare
ACMG Criteria Applied PM2
This variant is absent or extremely rare in population databases (PM2 criteria applies).

ClinVar

Open
Classification
Likely Pathogenic
2 publications
Publications List
PMID: 29394989

Data used in classification: The frequency of this variant is 0/138,632 individuals (gnomAD) (PM2_mod). This variant is predicted deleterious on AlignGVGD (class: C65), SIFT (Deleterious), Polyphen2 HumVar (probably damaging) and CADD (22.1) (PP3_sup). The variant is in the DNA-binding domain of BRCA2 (PM1_sup). In the VarCall Bayesian statistical model for VUS classification using functional assay data (Guidugli et al Am J Hum Genet 2018; 102:233-248, Couch Lab), the variant has a probability of being deleterious of 0.98 and an overall classification of pathogenic (PS3_strong). Data not used in classification: There are additional reports of this variant in ClinVar (2), BIC (1), and BRCA2 LOVD (1).

PMID: 12228710

The p.W2788R variant (also known as c.8362T>C), located in coding exon 18 of the BRCA2 gene, results from a T to C substitution at nucleotide position 8362. The tryptophan at codon 2788 is replaced by arginine, an amino acid with dissimilar properties. This variant was non-functional in multiple homology-directed DNA repair (HDR) assays (Guidugli L et al. Am. J. Hum. Genet. 2018 02;102(2):233-248; Richardson ME et al. Am J Hum Genet, 2021 Mar;108:458-468). Based on internal structural analysis, this alteration is likely to disrupt the local structure (Ambry internal data; Yang H et al. Science, 2002 Sep;297:1837-48). This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. This variant is considered to be rare based on population cohorts in the Genome Aggregation Database (gnomAD). Based on the majority of available evidence to date, this variant is likely to be pathogenic.

PMID: 29884841

In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. This variant has been reported to affect BRCA2 protein function (PMID: 29884841, 29394989). This variant has been reported in individuals in the Breast Cancer Information Core database (PMID: 10923033). ClinVar contains an entry for this variant (Variation ID: 52563). This variant is not present in population databases (ExAC no frequency). This sequence change replaces tryptophan with arginine at codon 2788 of the BRCA2 protein (p.Trp2788Arg). The tryptophan residue is highly conserved and there is a moderate physicochemical difference between tryptophan and arginine.

Clinical Statement

"This variant has been reported in ClinVar as Uncertain significance (2 clinical laboratories) and as Likely pathogenic (2 clinical laboratories) and as Likely Pathogenic by ClinGen ENIGMA BRCA1 and BRCA2 Variant Curation Expert Panel, ClinGen expert panel."

COSMIC Somatic Evidence

Open
COSMIC ID
Recurrence
0 occurrences
PM1 Criteria
Not Applied
COSMIC Database Preview
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Functional Impact & Domains

Functional Domain

Hotspot Status
Not a hotspot
Domain Summary
This variant is not located in a mutational hotspot or critical domain.
Related Variants in This Domain
No evidence of other pathogenic variants at this position in gene BRCA2.

Functional Studies & Therapeutic Relevance

Functional Summary

Error in OpenAI Consolidation. OncoKB: BRCA2W2788RBRCA2W2788RSomaticNCBI Gene:675|Show additional gene information Variant OverviewBRCA2, a tumor suppressor involved in the DNA damage response, is mutated in various cancer types.The BRCA2 W2788R mutation is likely oncogenic.Hide mutation effect description The BRCA2 W2788R mutation is located in the DNA-binding domain of the protein. Expression of this mutation in a BRCA-deficient cell line demonstrated that it is likely inactivating as measured by decreased homologous recombination (HR) DNA-repair activity in an in vitro homology-directed DNA repair (HDR) assay compared to wildtype BRCA2 and BRCA2-negative controls (PMID: 29394989). In vitro studies have demonstrated that this mutation is inactivating as measured by loss of HDR in an in vitro HDR assay (PMID: 35736817). Germline BRCA2 W2788R mutations are considered likely pathogenic by the ACMG framework classification (PMID: 35736817). JAX-CKB: No results found

Database Previews
OncoKB
OncoKB Preview
JAX-CKB
JAX-CKB Preview

Click on previews to view full database entries. External databases may require institutional access.

Computational Analysis

Pathogenicity Predictions

SpliceAI
Predictor Consensus
Mixed/VUS
PP3 Applied
No
REVEL Score
0.0
Threshold: ≥0.75 = PP3 applied

SpliceAI Scores

Window: ±500bp
Effect Type Score Position
- Acceptor Loss (AL) 0.03 68 bp
- Donor Loss (DL) 0.0 396 bp
+ Acceptor Gain (AG) 0.0 -30 bp
+ Donor Gain (DG) 0.01 125 bp
High impact (≥0.5) Medium impact (0.2-0.49) Low impact (<0.2)

VCEP Guidelines

Applied ACMG/AMP Criteria (VCEP Specific)

Filter Criteria:
PS3

PS3 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

PM2

PM2 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

PP5

PP5 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)

BP4

BP4 (Unknown (Pre-LLM))

From pre-LLM assessment (LLM Failed)